• Media type: E-Article
  • Title: Measuring Ankle Instability in Pediatric Charcot-Marie-Tooth Disease
  • Contributor: Mandarakas, Melissa; Hiller, Claire E.; Rose, Kristy J.; Burns, Joshua
  • Published: SAGE Publications, 2013
  • Published in: Journal of Child Neurology, 28 (2013) 11, Seite 1456-1462
  • Language: English
  • DOI: 10.1177/0883073813488676
  • ISSN: 0883-0738; 1708-8283
  • Origination:
  • Footnote:
  • Description: Children with Charcot-Marie-Tooth disease frequently suffer ankle sprain and experience chronic ankle instability; however, no pediatric self-reported measures of chronic ankle instability exist. The aim was to modify and validate the most reliable measure of chronic ankle instability in adults: the Cumberland Ankle Instability Tool. The Cumberland Ankle Instability Tool–Youth was tested for reliability, construct validity, and sensitivity to discriminate between 104 children aged 8 to 16 years: 31 children with Charcot-Marie-Tooth disease, 31 unaffected children with a history of ankle sprains, and 42 controls. Children with Charcot-Marie-Tooth disease had lower scores compared to unaffected children with a history of sprains (χ2= 15.10; P < .001) and controls (χ2= 33.69; P < .001). Scores moderately correlated to visual analog scale scores of ankle steadiness ( rs= 0.684; P < .001), and “good” test-retest reliability was identified (ICC2,1= 0.73). The Cumberland Ankle Instability Tool–Youth demonstrated excellent sensitivity and construct validity, identifying chronic ankle instability as a common problem for children with Charcot-Marie-Tooth disease.