• Medientyp: E-Artikel
  • Titel: Microtubule Destabilization and Nuclear Entry Are Sequential Steps Leading to Toxicity in Huntington's Disease
  • Beteiligte: Trushina, Eugenia; Heldebrant, Michael P.; Perez-Terzic, Carmen M.; Bortolon, Ryan; Kovtun, Irina V.; Badger, John D.; Terzic, Andre; Estévez, Alvaro; Windebank, Anthony J.; Dyer, Roy B.; Yao, Janet; McMurray, Cynthia T.
  • Erschienen: National Academy of Sciences, 2003
  • Erschienen in: Proceedings of the National Academy of Sciences of the United States of America
  • Sprache: Englisch
  • ISSN: 0027-8424
  • Schlagwörter: Biological Sciences
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  • Beschreibung: <p>There has been a longstanding debate regarding the role of proteolysis in Huntington's disease. The toxic peptide theory posits that N-terminal cleavage fragments of mutant Huntington's disease protein [mutant huntingtin (mhtt)] enter the nucleus to cause transcriptional dysfunction. However, recent data suggest a second model in which proteolysis of full-length mhtt is inhibited. Importantly, the two competing theories differ with respect to subcellular distribution of mhtt at initiation of toxicity: nuclear if cleaved and cytoplasmic in the absence of cleavage. Using quantitative single-cell analysis and time-lapse imaging, we show here that transcriptional dysfunction is "downstream" of cytoplasmic dysfunction. Primary and reversible toxic events involve destabilization of microtubules mediated by full-length mhtt before cleavage. Restoration of microtubule structure by taxol inhibits nuclear entry and increases cell survival.</p>
  • Zugangsstatus: Freier Zugang